清晨好,您是今天最早来到科研通的研友!由于当前在线用户较少,发布求助请尽量完整地填写文献信息,科研通机器人24小时在线,伴您科研之路漫漫前行!

Sanfilippo syndrome type B: Analysis of patients diagnosed by the MPS Brazil Network

医学 类型(生物学) 计算机科学 生物 生态学
作者
Yorran Hardman Araújo Montenegro,Carolina Fischinger Moura de Souza,Francyne Kubaski,Franciele Barbosa Trapp,Maira Graeff Burin,Kristiane Michelin‐Tirelli,Sandra Leistner‐Segal,Ana Carolina Brusius‐Facchin,Fernanda Silva Medeiros,Luciana Giugliani,Erlane Marques Ribeiro,Charles Marques Lourenço,Augusto César Cardoso‐dos‐Santos,Márcia Gonçalves Ribeiro,Chong Ae Kim,Matheus Augusto Araújo Castro,Emília Katiane Embiruçu,Carlos Eduardo Steiner,Maria Lucia Castro Moreira,Hector Quintero Montano
出处
期刊:American Journal of Medical Genetics [Wiley]
卷期号:188 (3): 760-767 被引量:5
标识
DOI:10.1002/ajmg.a.62572
摘要

Abstract Mucopolysaccharidosis type IIIB is a rare autosomal recessive disorder characterized by deficiency of the enzyme N‐acetyl‐alpha‐ d ‐glucosaminidase (NAGLU), caused by biallelic pathogenic variants in the NAGLU gene, which leads to storage of heparan sulfate and a series of clinical consequences which hallmark is neurodegeneration. In this study clinical, epidemiological, and biochemical data were obtained from MPS IIIB patients diagnosed from 2004–2019 by the MPS Brazil Network (“Rede MPS Brasil”), which was created with the goal to provide an easily accessible and comprehensive investigation of all MPS types. One hundred and ten MPS IIIB patients were diagnosed during this period. Mean age at diagnosis was 10.9 years. Patients were from all over Brazil, with a few from abroad, with a possible cluster of MPS IIIB identified in Ecuador. All patients had increased urinary levels of glycosaminoglycans and low NAGLU activity in blood. Main clinical symptoms reported at diagnosis were coarse facies and neurocognitive regression. The most common variant was p.Leu496Pro (30% of alleles). MPS IIIB seems to be relatively frequent in Brazil, but patients are diagnosed later than in other countries, and reasons for that probably include the limited awareness about the disease by health professionals and the difficulties to access diagnostic tests, factors that the MPS Brazil Network is trying to mitigate.

科研通智能强力驱动
Strongly Powered by AbleSci AI
科研通是完全免费的文献互助平台,具备全网最快的应助速度,最高的求助完成率。 对每一个文献求助,科研通都将尽心尽力,给求助人一个满意的交代。
实时播报
Shelly_ming完成签到,获得积分10
4秒前
14and15完成签到 ,获得积分10
9秒前
楠瓜完成签到,获得积分10
12秒前
leapper完成签到 ,获得积分10
13秒前
坦率雪枫完成签到 ,获得积分10
14秒前
charry完成签到,获得积分10
15秒前
Ava应助科研通管家采纳,获得10
15秒前
小蘑菇应助科研通管家采纳,获得10
15秒前
格格完成签到,获得积分10
19秒前
bwx完成签到,获得积分10
35秒前
楠瓜发布了新的文献求助10
43秒前
想多多发顶刊完成签到 ,获得积分10
47秒前
zhangwenjie完成签到 ,获得积分10
48秒前
53秒前
活着毕业完成签到 ,获得积分10
54秒前
Robin完成签到 ,获得积分10
55秒前
英俊小兔子完成签到,获得积分10
56秒前
柯彦完成签到 ,获得积分10
57秒前
粗暴的镜子完成签到,获得积分10
59秒前
凌泉完成签到 ,获得积分10
1分钟前
郭长银完成签到 ,获得积分10
1分钟前
三分之一星辰完成签到 ,获得积分10
1分钟前
刘丰完成签到 ,获得积分10
1分钟前
兴钬完成签到 ,获得积分0
1分钟前
幽默滑板完成签到 ,获得积分10
1分钟前
兜有米完成签到 ,获得积分10
1分钟前
好牛完成签到,获得积分10
1分钟前
kryptonite完成签到 ,获得积分10
1分钟前
Benhnhk21完成签到,获得积分10
1分钟前
GoriaChan完成签到 ,获得积分10
1分钟前
万能图书馆应助好牛采纳,获得10
1分钟前
pengyh8完成签到 ,获得积分10
1分钟前
xiuxiu125完成签到,获得积分10
1分钟前
1分钟前
忧郁荔枝完成签到 ,获得积分10
1分钟前
好牛发布了新的文献求助10
1分钟前
king完成签到 ,获得积分10
2分钟前
少年完成签到 ,获得积分10
2分钟前
mzhang2完成签到 ,获得积分10
2分钟前
任性铅笔完成签到 ,获得积分10
2分钟前
高分求助中
(应助此贴封号)【重要!!请各用户(尤其是新用户)详细阅读】【科研通的精品贴汇总】 10000
AnnualResearch andConsultation Report of Panorama survey and Investment strategy onChinaIndustry 1000
卤化钙钛矿人工突触的研究 1000
Engineering for calcareous sediments : proceedings of the International Conference on Calcareous Sediments, Perth 15-18 March 1988 / edited by R.J. Jewell, D.C. Andrews 1000
Continuing Syntax 1000
Signals, Systems, and Signal Processing 610
2026 Hospital Accreditation Standards 500
热门求助领域 (近24小时)
化学 材料科学 医学 生物 纳米技术 工程类 有机化学 化学工程 生物化学 计算机科学 物理 内科学 复合材料 催化作用 物理化学 光电子学 电极 细胞生物学 基因 无机化学
热门帖子
关注 科研通微信公众号,转发送积分 6262544
求助须知:如何正确求助?哪些是违规求助? 8084657
关于积分的说明 16891455
捐赠科研通 5333187
什么是DOI,文献DOI怎么找? 2838925
邀请新用户注册赠送积分活动 1816335
关于科研通互助平台的介绍 1670049